The red blood cell proteome and interactome identify a Band 3-BLVRB axis regulating hypoxic metabolic adaptation

A Aaron Vahe Issaian (University of Colorado Anschutz Medical Campus, Aurora, Colorado, United States) M Monika Dzieciatkowska S Shaun Bevers (University of Colorado - Anschutz Medical Campus, Aurora, Colorado, United States) Z Zohreh Safari (University of Maryland School of Medicine, Baltimore, Maryland, United States) A Ariel M Hay (University of Virginia, Charlottesville, Virginia, United States) F Francesca I Cendali (University of Colorado Anschutz Medical Campus, Aurora, Colorado, United States) A Amy Argabright (University of Colorado Anschutz Medical Campus, Aurora, CO, USA, Aurora, Colorado, United States) S Stephen C Rogers (University of Maryland School of Medicine, Baltimore, Maryland, United States) A Anthony J Saviola (University of Colorado Anschutz Medical Campus, Aurora, Colorado, United States) J Jasmina S Redzic (University of Colorado Denver, Aurora, Colorado, United States) E Eric Wartchow (Children's Hospital Colorado, Aurora, Colorado, United States) J Julie Reisz Haines (University of Colorado, Anschutz Medical Center, Aurora, Colorado, United States) G Gregory R Keele (RTI International, Research Triangle Park, North Carolina, United States) Z Zachary B Haiman (University of Colorado Denver - Anschutz Medical Campus, Denver, Colorado, United States) T Travis Nemkov D Daniel Stephenson C Christina Lisk (University of Colorado Anschutz Medical Campus, Aurora, Colorado, United States) F Francesca Vallese B Bernhard O. Palsson (University of California-San Diego School of Medicine, La Jolla, California, United States) S S Bruce King (Wake Forest University, Winston-Salem, North Carolina, United States) G Grier P Page (RTI International, Atlanta, Georgia, United States) A Allan Doctor (University of Maryland School of Medicine, Baltimore, Maryland, United States) K Krystalyn E Hudson (Columbia University, New York, New York, United States) K Kirk C Hansen (University of Colorado Anschutz Medical Campus School of Medicine, Aurora, Colorado, United States) D David C. Irwin (University of Colorado Health Science Center, Aurora, Colorado, United States) N Narla Mohandas J James C Zimring (Canadian Blood Services, Ottawa, Ontario, Canada) E Elan Z Eisenmesser (University of Colorado - Anschutz Medical Campus, Colorado, Colorado, United States) A Angelo D'Alessandro

Abstract

Red blood cells (RBCs) are transcriptionally silent yet dynamically remodel metabolism in response to oxygen tension. Using ultra-pure human RBCs, we generated the deepest contamination-free proteome to date (3,775 proteins) and mapped the oxygen-dependent interactome. These datasets reveal an oxygen-responsive metabolon centered on the Band 3 (SLC4A1) N-terminus. We identify biliverdin reductase B (BLVRB) as a previously unrecognized Band 3 interactor that dissociates under hypoxia, coincident with increased Band 3-deoxyhemoglobin contacts. This reversible assembly functions as an oxygen-sensitive switch coordinating redox and glycolytic remodeling. Humanized mice lacking Band 3 N-terminal segments exhibit impaired oxygen-dependent regulation of BLVRB binding to band 3, impaired hypoxic activation of glycolysis, reduced 2,3-bisphosphoglycerate synthesis, and diminished exercise tolerance, demonstrating physiological relevance. Population-scale cis-pQTLs for SLC4A1 and BLVRB suggest functions beyond canonical heme catabolism. Mechanistically, biochemical analyses in vitro suggest that hemoglobin β (HBB), Band 3, and BLVRB can undergo S-nitrosation and may participate in trans-nitrosation reactions with the glycolytic enzyme GAPDH, whose modification at C152 inhibits enzymatic activity in vitro. Collectively, these findings define a Band 3-BLVRB axis that integrates oxygen-dependent protein interactions with thiol-based redox chemistry, providing a framework for understanding how an anucleate cell achieves metabolic adaptability through reversible protein-protein interactions and post-translational modification. These findings suggest that perturbation of the Band 3-BLVRB axis may influence oxygen delivery and metabolic flexibility during hypoxic stress, with potential relevance to high-altitude adaptation, exercise physiology, and cardiopulmonary disease.

Article Details

Journal Blood
Volume / Issue Vol. 1, Issue 1
Published June 01, 2026
ISSN 0006-4971
Publisher Elsevier BV

Journal Info

Blood

Elsevier BV

ISSN: 0006-4971 Health Sciences

Authors (29)

A

Aaron Vahe Issaian

University of Colorado Anschutz Medical Campus, Aurora, Colorado, United States

M

Monika Dzieciatkowska

S

Shaun Bevers

University of Colorado - Anschutz Medical Campus, Aurora, Colorado, United States

Z

Zohreh Safari

University of Maryland School of Medicine, Baltimore, Maryland, United States

A

Ariel M Hay

University of Virginia, Charlottesville, Virginia, United States

F

Francesca I Cendali

University of Colorado Anschutz Medical Campus, Aurora, Colorado, United States

A

Amy Argabright

University of Colorado Anschutz Medical Campus, Aurora, CO, USA, Aurora, Colorado, United States

S

Stephen C Rogers

University of Maryland School of Medicine, Baltimore, Maryland, United States

A

Anthony J Saviola

University of Colorado Anschutz Medical Campus, Aurora, Colorado, United States

J

Jasmina S Redzic

University of Colorado Denver, Aurora, Colorado, United States

E

Eric Wartchow

Children's Hospital Colorado, Aurora, Colorado, United States

J

Julie Reisz Haines

University of Colorado, Anschutz Medical Center, Aurora, Colorado, United States

G

Gregory R Keele

RTI International, Research Triangle Park, North Carolina, United States

Z

Zachary B Haiman

University of Colorado Denver - Anschutz Medical Campus, Denver, Colorado, United States

T

Travis Nemkov

D

Daniel Stephenson

C

Christina Lisk

University of Colorado Anschutz Medical Campus, Aurora, Colorado, United States

F

Francesca Vallese

B

Bernhard O. Palsson

University of California-San Diego School of Medicine, La Jolla, California, United States

S

S Bruce King

Wake Forest University, Winston-Salem, North Carolina, United States

G

Grier P Page

RTI International, Atlanta, Georgia, United States

A

Allan Doctor

University of Maryland School of Medicine, Baltimore, Maryland, United States

K

Krystalyn E Hudson

Columbia University, New York, New York, United States

K

Kirk C Hansen

University of Colorado Anschutz Medical Campus School of Medicine, Aurora, Colorado, United States

D

David C. Irwin

University of Colorado Health Science Center, Aurora, Colorado, United States

N

Narla Mohandas

J

James C Zimring

Canadian Blood Services, Ottawa, Ontario, Canada

E

Elan Z Eisenmesser

University of Colorado - Anschutz Medical Campus, Colorado, Colorado, United States

A

Angelo D'Alessandro