Mitochondrial ABHD11 inhibition drives sterol metabolism to modulate T-cell effector function

B Benjamin J. Jenkins Y Yasmin R. Jenkins F Fernando M. Ponce-Garcia C Chloe Moscrop I Iain A. Perry M Matthew D. Hitchings A Alejandro H. Uribe F Federico Bernuzzi S Simon Eastham J James G. Cronin A Ardena Berisha A Alexandra Howell J Joanne Davies J Julianna Blagih M Marta Williams M Morgan Marsden D Douglas J. Veale L Luke C. Davies M Micah Niphakis D David K. Finlay L Linda V. Sinclair B Benjamin F. Cravatt A Andrew E. Hogan J James A. Nathan I Ian R. Humphreys U Ursula Fearon D David Sumpton J Johan Vande Voorde G Goncalo Dias do Vale J Jeffrey G. McDonald (Department of Molecular Genetics, University of Texas Southwestern Medical Center) G Gareth W. Jones J James A. Pearson E Emma E. Vincent N Nicholas Jones

Abstract

Abstract α/β-hydrolase domain-containing protein 11 (ABHD11) is a mitochondrial hydrolase that maintains the catalytic function of α-ketoglutarate dehydrogenase (α-KGDH), and its expression in CD4 + T-cells has been linked to remission status in rheumatoid arthritis (RA). However, the importance of ABHD11 in regulating T-cell metabolism and function is yet to be explored. Here, we show that pharmacological inhibition of ABHD11 dampens cytokine production by human and mouse T-cells. Mechanistically, the anti-inflammatory effects of ABHD11 inhibition are attributed to increased 24,25-epoxycholesterol (24,25-EC) biosynthesis and subsequent liver X receptor (LXR) activation, which arise from a compromised TCA cycle. The impaired cytokine profile established by ABHD11 inhibition is extended to two patient cohorts of autoimmunity. Importantly, using murine models of accelerated type 1 diabetes (T1D), we show that targeting ABHD11 suppresses cytokine production in antigen-specific T-cells and delays the onset of diabetes in vivo in female mice. Collectively, our work provides pre-clinical evidence that ABHD11 is an encouraging drug target in T-cell-mediated inflammation.

Article Details

Volume / Issue Vol. 16, Issue 1
Published November 03, 2025
ISSN 2041-1723
Publisher Nature Portfolio

Journal Info

Nature Communications

Nature Portfolio

ISSN: 2041-1723 Open Access Life Sciences

Authors (34)

B

Benjamin J. Jenkins

Y

Yasmin R. Jenkins

F

Fernando M. Ponce-Garcia

C

Chloe Moscrop

I

Iain A. Perry

M

Matthew D. Hitchings

A

Alejandro H. Uribe

F

Federico Bernuzzi

S

Simon Eastham

J

James G. Cronin

A

Ardena Berisha

A

Alexandra Howell

J

Joanne Davies

J

Julianna Blagih

M

Marta Williams

M

Morgan Marsden

D

Douglas J. Veale

L

Luke C. Davies

M

Micah Niphakis

D

David K. Finlay

L

Linda V. Sinclair

B

Benjamin F. Cravatt

A

Andrew E. Hogan

J

James A. Nathan

I

Ian R. Humphreys

U

Ursula Fearon

D

David Sumpton

J

Johan Vande Voorde

G

Goncalo Dias do Vale

J

Jeffrey G. McDonald

Department of Molecular Genetics, University of Texas Southwestern Medical Center

G

Gareth W. Jones

J

James A. Pearson

E

Emma E. Vincent

N

Nicholas Jones