IAP dependency of T-cell prolymphocytic leukemia identified by high-throughput drug screening

M Marcel Fabian Pohly (1Department of Medical Oncology and Hematology, University Hospital and University of Zurich, Zurich, Switzerland) K Kerstin Putzker (3Chemical Biology Core Facility, European Molecular Biology Laboratory, Heidelberg, Germany) S Sebastian Scheinost (4Molecular Therapy in Hematology and Oncology, Department of Translational Oncology, National Center for Tumor Diseases and German Cancer Research Centre, Heidelberg, Germany) L Lena Ben Taarit (4Molecular Therapy in Hematology and Oncology, Department of Translational Oncology, National Center for Tumor Diseases and German Cancer Research Centre, Heidelberg, Germany) T Tatjana Walther (4Molecular Therapy in Hematology and Oncology, Department of Translational Oncology, National Center for Tumor Diseases and German Cancer Research Centre, Heidelberg, Germany) S Sandra Kummer (1Department of Medical Oncology and Hematology, University Hospital and University of Zurich, Zurich, Switzerland) T Tobias Wertheimer M Minqi Lin (5Department of Inflammation Research, Institute of Experimental Immunology, University of Zurich, Zurich, Switzerland) T Thi Huong Lan Do (1Department of Medical Oncology and Hematology, University Hospital and University of Zurich, Zurich, Switzerland) K Kristina Handler J Jan Michler (2Department of Biosystems Science and Engineering, ETH Zurich, Basel, Switzerland) J Jarno Kivioja (1Department of Medical Oncology and Hematology, University Hospital and University of Zurich, Zurich, Switzerland) K Karsten Bach (2Department of Biosystems Science and Engineering, ETH Zurich, Basel, Switzerland) S Samanta Kisele J James Kim S Sascha Dietrich B Beat Bornhauser W Wendy Wei-Lynn Wong (10Department of Molecular Life Sciences, University of Zurich, Zurich, Switzerland) B Burkhard Becher A Andreas Moor (2Department of Biosystems Science and Engineering, ETH Zurich, Basel, Switzerland) J Joe Lewis (3Chemical Biology Core Facility, European Molecular Biology Laboratory, Heidelberg, Germany) X Xenia Ficht (2Department of Biosystems Science and Engineering, ETH Zurich, Basel, Switzerland) J Junyan Lu W Wolfgang Huber T Thorsten Zenz

Abstract

Abstract T-cell prolymphocytic leukemia (T-PLL) is an aggressive lymphoid malignancy with limited treatment options. To discover new treatment targets for T-PLL, we performed high-throughput drug sensitivity screening on 30 primary patient samples ex vivo. After screening >2800 unique compounds, we found T-PLL to be more resistant to most drug classes, including chemotherapeutics, than other blood cancers. Furthermore, we discovered previously unreported vulnerabilities of T-PLL. T-PLL cells exhibited a particular sensitivity to drugs targeting autophagy (thapsigargin and bafilomycin A1), nuclear export (selinexor), and inhibitor of apoptosis proteins (IAPs; birinapant), sensitivities that were also shared by other T-cell malignancies. Through bulk and single-cell RNA sequencing, we found these compounds to activate the Toll-like receptor (bafilomycin A1), p53 (selinexor), and tumor necrosis factor α (TNF-α)/NF-κB signaling pathways (birinapant) in T-PLL cells. Focusing on birinapant for its potential in drug repurposing, we uncovered that IAP inhibitor–induced cell death was primarily necroptotic and dependent on TNF-α. Through spectral flow cytometry, we confirmed the absence of cleaved caspase-3 in IAP inhibitor–treated T-PLL cells and show that IAP inhibition reduces the proliferation of T-PLL cells stimulated ex vivo, while showing only a limited effect on nonmalignant T-cells. In summary, our study maps the drug sensitivity of T-PLL across a broad range of targets and identifies new therapeutic approaches for T-PLL by targeting IAPs, exportin 1, and autophagy, highlighting potential candidates for drug repurposing and novel treatment strategies.

Article Details

Journal Blood
Volume / Issue Vol. 145, Issue 20
Published May 15, 2025
Pages 2336-2352
ISSN 0006-4971
Publisher Elsevier BV

Journal Info

Blood

Elsevier BV

ISSN: 0006-4971 Health Sciences

Authors (25)

M

Marcel Fabian Pohly

1Department of Medical Oncology and Hematology, University Hospital and University of Zurich, Zurich, Switzerland

K

Kerstin Putzker

3Chemical Biology Core Facility, European Molecular Biology Laboratory, Heidelberg, Germany

S

Sebastian Scheinost

4Molecular Therapy in Hematology and Oncology, Department of Translational Oncology, National Center for Tumor Diseases and German Cancer Research Centre, Heidelberg, Germany

L

Lena Ben Taarit

4Molecular Therapy in Hematology and Oncology, Department of Translational Oncology, National Center for Tumor Diseases and German Cancer Research Centre, Heidelberg, Germany

T

Tatjana Walther

4Molecular Therapy in Hematology and Oncology, Department of Translational Oncology, National Center for Tumor Diseases and German Cancer Research Centre, Heidelberg, Germany

S

Sandra Kummer

1Department of Medical Oncology and Hematology, University Hospital and University of Zurich, Zurich, Switzerland

T

Tobias Wertheimer

M

Minqi Lin

5Department of Inflammation Research, Institute of Experimental Immunology, University of Zurich, Zurich, Switzerland

T

Thi Huong Lan Do

1Department of Medical Oncology and Hematology, University Hospital and University of Zurich, Zurich, Switzerland

K

Kristina Handler

J

Jan Michler

2Department of Biosystems Science and Engineering, ETH Zurich, Basel, Switzerland

J

Jarno Kivioja

1Department of Medical Oncology and Hematology, University Hospital and University of Zurich, Zurich, Switzerland

K

Karsten Bach

2Department of Biosystems Science and Engineering, ETH Zurich, Basel, Switzerland

S

Samanta Kisele

J

James Kim

S

Sascha Dietrich

B

Beat Bornhauser

W

Wendy Wei-Lynn Wong

10Department of Molecular Life Sciences, University of Zurich, Zurich, Switzerland

B

Burkhard Becher

A

Andreas Moor

2Department of Biosystems Science and Engineering, ETH Zurich, Basel, Switzerland

J

Joe Lewis

3Chemical Biology Core Facility, European Molecular Biology Laboratory, Heidelberg, Germany

X

Xenia Ficht

2Department of Biosystems Science and Engineering, ETH Zurich, Basel, Switzerland

J

Junyan Lu

W

Wolfgang Huber

T

Thorsten Zenz