Covered Stent Correction for Sinus Venosus Atrial Septal Defects, an Emerging Alternative to Surgical Repair: Results of an International Registry

E Eric Rosenthal (Paediatric and Adult Congenital Heart Disease, Evelina London Children’s Hospital, Guy’s & St Thomas’ Hospital Trust, UK (E.R., S.A.Q., M.J., S.-F.Y., S.K.).) S Shakeel A. Qureshi (Paediatric and Adult Congenital Heart Disease, Evelina London Children’s Hospital, Guy’s & St Thomas’ Hospital Trust, UK (E.R., S.A.Q., M.J., S.-F.Y., S.K.).) K Kothandam Sivakumar (Department of Pediatric Cardiology, Institute of Cardio Vascular Diseases, Madras Medical Mission, Chennai, India (K.S., P.S., P. Thejaswi).) M Matthew Jones S San-Fui Yong (Paediatric and Adult Congenital Heart Disease, Evelina London Children’s Hospital, Guy’s & St Thomas’ Hospital Trust, UK (E.R., S.A.Q., M.J., S.-F.Y., S.K.).) S Saleha Kabir (Paediatric and Adult Congenital Heart Disease, Evelina London Children’s Hospital, Guy’s & St Thomas’ Hospital Trust, UK (E.R., S.A.Q., M.J., S.-F.Y., S.K.).) P Pramod Sagar (Department of Pediatric Cardiology, Institute of Cardio Vascular Diseases, Madras Medical Mission, Chennai, India (K.S., P.S., P. Thejaswi).) P Puthiyedath Thejaswi (Department of Pediatric Cardiology, Institute of Cardio Vascular Diseases, Madras Medical Mission, Chennai, India (K.S., P.S., P. Thejaswi).) S Sébastien Hascoet C Clement Batteux (Department of Congenital Heart Diseases, Centre de Reference Cardiopathies Congenitales Complexes M3C, Hospital Marie Lannelongue, Groupe Hospitalier Paris, Saint Joseph, Universite Paris-Saclay, Paris, France (S.H., C.B.).) Y Younes Boudjemline (Sidra Heart Center, Sidra Medicine, Doha, Qatar (Y.B., Z.M.H.).) Z Ziyad M. Hijazi (Sidra Heart Center, Sidra Medicine, Doha, Qatar (Y.B., Z.M.H.).) J Jamil A. Aboulhosn D Daniel S. Levi (Division of Pediatric Cardiology, Mattel Children’s Hospital at UCLA, Los Angeles, CA (D.S.L., M.M.S.).) M Morris M. Salem (Division of Pediatric Cardiology, Mattel Children’s Hospital at UCLA, Los Angeles, CA (D.S.L., M.M.S.).) E Edwin Francis (Aster Medcity Hospital, Kochi, India (E.F.).) A Aleksander Kempny (Adult Congenital Heart Disease, Royal Brompton Hospital, London, UK (A.K., A.F., C.B.-R.).) A Alain Fraisse (Cardiovascular Intervention Research Center, Rajaie Cardiovascular Medical and Research Institute, Iran University of Medical Sciences, Tehran (A.F., Z.K.).) C Carles Bautista-Rodriguez (Adult Congenital Heart Disease, Royal Brompton Hospital, London, UK (A.K., A.F., C.B.-R.).) K Kevin Walsh D Damien Kenny (Department of Cardiology, Mater Misericordiae University Hospital, Dublin, Ireland (K.W., D.K., B.T.).) B Brian Traynor (Department of Cardiology, Mater Misericordiae University Hospital, Dublin, Ireland (K.W., D.K., B.T.).) S Salim N. Al Maskari (Paediatric Cardiology, National Heart Centre, Muscat, Oman (S.N.A.M.).) J James R. Bentham (Department of Congenital Cardiology, Leeds General Infirmary, UK (J.R.B.).) L László Környei (Gottsegen National Cardiovascular Center, Budapest, Hungary (L.K.).) M Muthukumaran C. Sivaprakasam (Department of Paediatric Cardiology, Apollo Children’s Hospital, Chennai, India (M.C.S.).) A Ata Firouzi (Adult Congenital Heart Disease, Royal Brompton Hospital, London, UK (A.K., A.F., C.B.-R.).) Z Zahra Khajali L Lee Benson (Labatt Family Heart Center, Hospital for Sick Children, Toronto General Hospital, University of Toronto School of Medicine, ON, Canada (L.B., M.O.).) M Mark Osten A Alban-Elouen Baruteau (Nantes Université, CHU Nantes, Department of Pediatric Cardiology and Pediatric Cardiac Surgery, FHU PRECICARE, France (A.-E.B.).) M Matthew A. Crystal (Congenital Interventional Catheterization, Columbia University Vagelos College of Physicians and Surgeons, Morgan Stanley Children’s Hospital of New York–Presbyterian, New York (M.A.C.).) T Thomas J. Forbes (Joe DiMaggio Children’s Hospital, Hollywood, FL (T.J.F.).) S Stanimir Georgiev (Department of Congenital Heart Diseases and Pediatric Cardiology, German Heart Center, Munich, Germany (S.G.).) H Horst Sievert (CardioVascular Center Frankfurt, Germany (H.S.).) D Do Nguyen Tin (Department of Pediatrics, University of Medicine and Pharmacy, Ho Chi Minh City, Vietnam (T.D.N.).) D Daniel Springmuller (Departamento de Cardiología Pediátrica, División de Pediatría, Facultad de Medicina, Pontificia Universidad Católica de Chile, Unidad de Cardiopatías Congénitas del Adulto, Instituto Nacional del Tórax, Santiago, Chile (D.S.).) A Anand Subramanian (Pediatric Cardiology, Sri Jayadeva Institute of Cardiovascular Sciences, Bangalore, India (A.S.).) H Hussein A.M. Abdullah (Ibn- Albitar Center for Cardiac Surgery, Baghdad, Iraq (H.A.M.A.).) R Radwa Bedair (Adult Congenital Cardiology, Bristol Heart Institute, UK (R.B.).) F Francisco Chamié (INTERCAT–Interventional Cardiology, Rio de Janeiro, Brazil (F.C.).) A Ahmet Celebi (Department of Pediatric Cardiology, Dr Siyami Ersek Hospital for Cardiology and Cardiovascular Surgery, Istanbul, Turkey (A.C.).) J Jesus Damsky Barbosa (Cardiology and Hemodynamics, Pedro de Elizalde Children’s Hospital, Buenos Aires, Argentina (J.D.B.).) P Pieter De Meester (University Hospitals Leuven, Leuven, Belgium) L Luca Giugno (IRCCS Policlinico San Donato, Milano, Italy (L.G.).) Z Zakaria Jalal (Department of Pediatric and Adult Congenital Cardiology, University Hospital of Bordeaux, France (Z.J.).) C Clement Karsenty (Pediatric and Congenital Cardiology, Children’s Hospital CHU Toulouse, Institut des Maladies Métaboliques et Cardiovasculaires, Université de Toulouse, Institut National de la Santé et de la Recherche Médicale (INSERM), U1048, Clinique Pasteur, France (C.K.).) A Anastasia Schleiger G Gregory Fleming (Division of Pediatric Cardiology, Duke University Medical Center, Durham, NC (G.F.).) A Andre Jakob (Department of Paediatric Cardiology and Paediatric Intensive Care, University Hospital, LMU Munich, Germany (A.J.).) T Tevfik Karagoaz (Department of Pediatric Cardiology, Faculty of Medicine, Hacettepe University, Ankara, Turkey (T.K.).) G Gur Mainzer (Pediatric Cardiology Department, Hadassah Medical Center, Jerusalem, Israel (G.M.).) G Gareth J. Morgan N Nazmi Narin S Shabana Shahanavaz (Department of Pediatrics Heart Institute, Cincinnati Children’s Hospital, University of Cincinnati College of Medicine, OH (S.S.).) Z Zachary L. Steinberg (Division of Cardiology, Department of Medicine, University of Washington Medical Center, Seattle (Z.L.S.).) O Osamah Aldoss (Division of Pediatric Cardiology, Stead Family Children’s Hospital, University of Iowa, Iowa City (O. Aldoss).) E Elnur Alizade (Kosuyolu Heart, Research and Education Hospital, Department of Cardiology, Istanbul, Turkey (E.A.).) O Oliver Aregullin (Congenital Cardiology, Congenital Heart Center, Spectrum Health Helen DeVos Children’s Hospital, Grand Rapids, MI (O. Aregullin).) H Hélène Bouvaist (Service de Cardiologie–CHU Grenoble Alpes, France (H.B.).) T Thilo Fleck (Department of Congenital Heart Disease and Pediatric Cardiology, University Heart Center Freiburg–Bad Krozingen, Medical Center, University of Freiburg, Germany (T.F.).) F François Godart S Sophie Malekzadeh-Milani P Paulo Motta (Interventional Cardiology, Home Hospital, Brasilia, Brazil (P.M.).) Ángel Sánchez-Recalde (Cardiology Department, University Hospital Ramón y Cajal, Madrid) J Juan Pablo Sandoval (Imaging and Intervention in Congenital and Structural Heart Disease, Ignacio Chavez National Institute of Cardiology, Mexico City, Mexico (J.P.S.).) W Weiyi Tan (Department of Chemistry) J John Thomson (UES, a BlueHalo Company) P Pablo Tomé Teixeirense (Hospital Fornecedores de Cana de Piracicaba, São Paulo, Brazil (P. Tome).) E Evan M. Zahn (Department of Pediatrics, The Smidt Heart Institute, Cedars Sinai Medical Center, Los Angeles, CA (E.M.Z.).)

Abstract

BACKGROUND: Covered stent correction for a sinus venosus atrial septal defect (SVASD) was first performed in 2009. This innovative approach was initially viewed as experimental and was reserved for highly selected patients with unusual anatomic variants. In 2016, increasing numbers of procedures began to be performed, and in several centers, it is now offered as a standard of care option alongside surgical repair. However, covered stent correction for SVASD is not recognized by regulatory authorities, and in the minds of many pediatric and adult congenital cardiologists and surgeons, the condition is viewed as treatable only by cardiac surgery with cardiopulmonary bypass. METHODS: In April 2023, all centers identified from international conferences, publications, and colleague networks to be undertaking covered stent correction for SVASD were invited to participate in a retrospective audit of their procedures. RESULTS: Data were received on 381 patients from 54 units over a 12-year period with 90% of procedures being performed over the past 5 years. Balloon-expandable stents (8 types) were used in the majority; self-expanding stents (4 types) were used in 4.5%. The commonest stent was the 10-zig covered Cheatham Platinum stent in 62% of cases. In 10 procedures, the stent embolized requiring surgical retrieval and repair of the defect, resulting in technically successful implantation in 371 of 381 (97.4%). Major complications (surgical drainage of tamponade, pacemaker implantation, surgery for pulmonary vein occlusion, and late stent removal) occurred in 5 patients (1.3%). Repeat catheterization to correct residual leaks was required in 7 patients (1.8%). Thus, 359 of 381 patients (94.2%) had successful correction without major complications or additional catheter interventions. CONCLUSIONS: This article details the exponential uptake of covered stent correction for SVASD during the past 5 years. Cardiopulmonary bypass was avoided in the majority of patients, and major complications were infrequent. Prospective registries with standardized definitions, inclusion criteria, and follow-up and comparative studies with surgery are now required to help support the extension of covered stent correction as an alternative standard-of-care option for patients with an SVASD.

Article Details

Journal Circulation
Volume / Issue Vol. 151, Issue 11
Published March 18, 2025
Pages 744-756
ISSN 0009-7322
Publisher Lippincott Williams & Wilkins

Journal Info

Circulation

Lippincott Williams & Wilkins

ISSN: 0009-7322 Health Sciences

Authors (70)

E

Eric Rosenthal

Paediatric and Adult Congenital Heart Disease, Evelina London Children’s Hospital, Guy’s & St Thomas’ Hospital Trust, UK (E.R., S.A.Q., M.J., S.-F.Y., S.K.).

S

Shakeel A. Qureshi

Paediatric and Adult Congenital Heart Disease, Evelina London Children’s Hospital, Guy’s & St Thomas’ Hospital Trust, UK (E.R., S.A.Q., M.J., S.-F.Y., S.K.).

K

Kothandam Sivakumar

Department of Pediatric Cardiology, Institute of Cardio Vascular Diseases, Madras Medical Mission, Chennai, India (K.S., P.S., P. Thejaswi).

M

Matthew Jones

S

San-Fui Yong

Paediatric and Adult Congenital Heart Disease, Evelina London Children’s Hospital, Guy’s & St Thomas’ Hospital Trust, UK (E.R., S.A.Q., M.J., S.-F.Y., S.K.).

S

Saleha Kabir

Paediatric and Adult Congenital Heart Disease, Evelina London Children’s Hospital, Guy’s & St Thomas’ Hospital Trust, UK (E.R., S.A.Q., M.J., S.-F.Y., S.K.).

P

Pramod Sagar

Department of Pediatric Cardiology, Institute of Cardio Vascular Diseases, Madras Medical Mission, Chennai, India (K.S., P.S., P. Thejaswi).

P

Puthiyedath Thejaswi

Department of Pediatric Cardiology, Institute of Cardio Vascular Diseases, Madras Medical Mission, Chennai, India (K.S., P.S., P. Thejaswi).

S

Sébastien Hascoet

C

Clement Batteux

Department of Congenital Heart Diseases, Centre de Reference Cardiopathies Congenitales Complexes M3C, Hospital Marie Lannelongue, Groupe Hospitalier Paris, Saint Joseph, Universite Paris-Saclay, Paris, France (S.H., C.B.).

Y

Younes Boudjemline

Sidra Heart Center, Sidra Medicine, Doha, Qatar (Y.B., Z.M.H.).

Z

Ziyad M. Hijazi

Sidra Heart Center, Sidra Medicine, Doha, Qatar (Y.B., Z.M.H.).

J

Jamil A. Aboulhosn

D

Daniel S. Levi

Division of Pediatric Cardiology, Mattel Children’s Hospital at UCLA, Los Angeles, CA (D.S.L., M.M.S.).

M

Morris M. Salem

Division of Pediatric Cardiology, Mattel Children’s Hospital at UCLA, Los Angeles, CA (D.S.L., M.M.S.).

E

Edwin Francis

Aster Medcity Hospital, Kochi, India (E.F.).

A

Aleksander Kempny

Adult Congenital Heart Disease, Royal Brompton Hospital, London, UK (A.K., A.F., C.B.-R.).

A

Alain Fraisse

Cardiovascular Intervention Research Center, Rajaie Cardiovascular Medical and Research Institute, Iran University of Medical Sciences, Tehran (A.F., Z.K.).

C

Carles Bautista-Rodriguez

Adult Congenital Heart Disease, Royal Brompton Hospital, London, UK (A.K., A.F., C.B.-R.).

K

Kevin Walsh

D

Damien Kenny

Department of Cardiology, Mater Misericordiae University Hospital, Dublin, Ireland (K.W., D.K., B.T.).

B

Brian Traynor

Department of Cardiology, Mater Misericordiae University Hospital, Dublin, Ireland (K.W., D.K., B.T.).

S

Salim N. Al Maskari

Paediatric Cardiology, National Heart Centre, Muscat, Oman (S.N.A.M.).

J

James R. Bentham

Department of Congenital Cardiology, Leeds General Infirmary, UK (J.R.B.).

L

László Környei

Gottsegen National Cardiovascular Center, Budapest, Hungary (L.K.).

M

Muthukumaran C. Sivaprakasam

Department of Paediatric Cardiology, Apollo Children’s Hospital, Chennai, India (M.C.S.).

A

Ata Firouzi

Adult Congenital Heart Disease, Royal Brompton Hospital, London, UK (A.K., A.F., C.B.-R.).

Z

Zahra Khajali

L

Lee Benson

Labatt Family Heart Center, Hospital for Sick Children, Toronto General Hospital, University of Toronto School of Medicine, ON, Canada (L.B., M.O.).

M

Mark Osten

A

Alban-Elouen Baruteau

Nantes Université, CHU Nantes, Department of Pediatric Cardiology and Pediatric Cardiac Surgery, FHU PRECICARE, France (A.-E.B.).

M

Matthew A. Crystal

Congenital Interventional Catheterization, Columbia University Vagelos College of Physicians and Surgeons, Morgan Stanley Children’s Hospital of New York–Presbyterian, New York (M.A.C.).

T

Thomas J. Forbes

Joe DiMaggio Children’s Hospital, Hollywood, FL (T.J.F.).

S

Stanimir Georgiev

Department of Congenital Heart Diseases and Pediatric Cardiology, German Heart Center, Munich, Germany (S.G.).

H

Horst Sievert

CardioVascular Center Frankfurt, Germany (H.S.).

D

Do Nguyen Tin

Department of Pediatrics, University of Medicine and Pharmacy, Ho Chi Minh City, Vietnam (T.D.N.).

D

Daniel Springmuller

Departamento de Cardiología Pediátrica, División de Pediatría, Facultad de Medicina, Pontificia Universidad Católica de Chile, Unidad de Cardiopatías Congénitas del Adulto, Instituto Nacional del Tórax, Santiago, Chile (D.S.).

A

Anand Subramanian

Pediatric Cardiology, Sri Jayadeva Institute of Cardiovascular Sciences, Bangalore, India (A.S.).

H

Hussein A.M. Abdullah

Ibn- Albitar Center for Cardiac Surgery, Baghdad, Iraq (H.A.M.A.).

R

Radwa Bedair

Adult Congenital Cardiology, Bristol Heart Institute, UK (R.B.).

F

Francisco Chamié

INTERCAT–Interventional Cardiology, Rio de Janeiro, Brazil (F.C.).

A

Ahmet Celebi

Department of Pediatric Cardiology, Dr Siyami Ersek Hospital for Cardiology and Cardiovascular Surgery, Istanbul, Turkey (A.C.).

J

Jesus Damsky Barbosa

Cardiology and Hemodynamics, Pedro de Elizalde Children’s Hospital, Buenos Aires, Argentina (J.D.B.).

P

Pieter De Meester

University Hospitals Leuven, Leuven, Belgium

L

Luca Giugno

IRCCS Policlinico San Donato, Milano, Italy (L.G.).

Z

Zakaria Jalal

Department of Pediatric and Adult Congenital Cardiology, University Hospital of Bordeaux, France (Z.J.).

C

Clement Karsenty

Pediatric and Congenital Cardiology, Children’s Hospital CHU Toulouse, Institut des Maladies Métaboliques et Cardiovasculaires, Université de Toulouse, Institut National de la Santé et de la Recherche Médicale (INSERM), U1048, Clinique Pasteur, France (C.K.).

A

Anastasia Schleiger

G

Gregory Fleming

Division of Pediatric Cardiology, Duke University Medical Center, Durham, NC (G.F.).

A

Andre Jakob

Department of Paediatric Cardiology and Paediatric Intensive Care, University Hospital, LMU Munich, Germany (A.J.).

T

Tevfik Karagoaz

Department of Pediatric Cardiology, Faculty of Medicine, Hacettepe University, Ankara, Turkey (T.K.).

G

Gur Mainzer

Pediatric Cardiology Department, Hadassah Medical Center, Jerusalem, Israel (G.M.).

G

Gareth J. Morgan

N

Nazmi Narin

S

Shabana Shahanavaz

Department of Pediatrics Heart Institute, Cincinnati Children’s Hospital, University of Cincinnati College of Medicine, OH (S.S.).

Z

Zachary L. Steinberg

Division of Cardiology, Department of Medicine, University of Washington Medical Center, Seattle (Z.L.S.).

O

Osamah Aldoss

Division of Pediatric Cardiology, Stead Family Children’s Hospital, University of Iowa, Iowa City (O. Aldoss).

E

Elnur Alizade

Kosuyolu Heart, Research and Education Hospital, Department of Cardiology, Istanbul, Turkey (E.A.).

O

Oliver Aregullin

Congenital Cardiology, Congenital Heart Center, Spectrum Health Helen DeVos Children’s Hospital, Grand Rapids, MI (O. Aregullin).

H

Hélène Bouvaist

Service de Cardiologie–CHU Grenoble Alpes, France (H.B.).

T

Thilo Fleck

Department of Congenital Heart Disease and Pediatric Cardiology, University Heart Center Freiburg–Bad Krozingen, Medical Center, University of Freiburg, Germany (T.F.).

F

François Godart

S

Sophie Malekzadeh-Milani

P

Paulo Motta

Interventional Cardiology, Home Hospital, Brasilia, Brazil (P.M.).

Ángel Sánchez-Recalde

Cardiology Department, University Hospital Ramón y Cajal, Madrid

J

Juan Pablo Sandoval

Imaging and Intervention in Congenital and Structural Heart Disease, Ignacio Chavez National Institute of Cardiology, Mexico City, Mexico (J.P.S.).

W

Weiyi Tan

Department of Chemistry

J

John Thomson

UES, a BlueHalo Company

P

Pablo Tomé Teixeirense

Hospital Fornecedores de Cana de Piracicaba, São Paulo, Brazil (P. Tome).

E

Evan M. Zahn

Department of Pediatrics, The Smidt Heart Institute, Cedars Sinai Medical Center, Los Angeles, CA (E.M.Z.).