CNS relapse in high-grade B-cell lymphoma with <i>MYC</i> and <i>BCL2</i> rearrangements and dark-zone signature–expressing DLBCL

W Waleed Alduaij (1Centre for Lymphoid Cancer, BC Cancer, Vancouver, BC, Canada) A Aixiang Jiang (1Centre for Lymphoid Cancer, British Columbia Cancer, Vancouver, BC, Canada) D Diego Villa (8Division of Medical Oncology, BC Cancer Centre for Lymphoid Cancer and The University of British Columbia, Vancouver, Canada) B Brett Collinge (1Centre for Lymphoid Cancer, BC Cancer, Vancouver, BC, Canada) S Susana Ben-Neriah (1Centre for Lymphoid Cancer, British Columbia Cancer, Vancouver, BC, Canada) M Merrill Boyle (1Centre for Lymphoid Cancer, British Columbia Cancer, Vancouver, BC, Canada) B Barbara Meissner (1Centre for Lymphoid Cancer, British Columbia Cancer, Vancouver, BC, Canada) L Laura K. Hilton (4Centre for Lymphoid Cancer, BC Cancer, Vancouver, BC, Canada) P Pedro Farinha (6BC Cancer, Vancouver, BC, Canada) G Graham W. Slack (6BC Cancer, Vancouver, BC, Canada) J Jeffrey W. Craig (Department of Pathology University of Virginia Medical Center Charlottesville Virginia USA) A Alina S. Gerrie (21BC Cancer Centre for Lymphoid Cancer, University of British Columbia, Vancouver, BC, Canada) C Ciara L. Freeman (7Department of Blood and Marrow Transplant and Cellular Immunotherapy, H. Lee Moffitt Cancer Center and Research Institute, Tampa, FL) A Andrew J. Mungall (5Canada’s Michael Smith Genome Sciences Centre, BC Cancer, Vancouver, BC, Canada) C Christian Steidl (5Centre for Lymphoid Cancer, British Columbia Cancer, Vancouver, Canada) L Laurie H. Sehn (8Division of Medical Oncology, BC Cancer Centre for Lymphoid Cancer and The University of British Columbia, Vancouver, Canada) D David W. Scott (5Centre for Lymphoid Cancer, British Columbia Cancer, Vancouver, Canada) K Kerry J. Savage (6BC Cancer, Vancouver, BC, Canada)

Abstract

Abstract High-grade B-cell lymphoma with MYC and BCL2 rearrangements (HGBCL-DH-BCL2), or “double-hit lymphoma,” has been associated with a high risk of central nervous system (CNS) relapse. However, historic estimates are impacted by selection bias. We report CNS relapse rates associated with HGBCL-DH-BCL2 from a population-based cohort with complete fluorescence in situ hybridization testing, as well as diffuse large B-cell lymphoma morphology (DLBCL) tumors expressing the dark-zone gene expression signature (DZsig), which was originally derived from HGBCL-DH-BCL2. The 2-year CNS relapse risk in HGBCL-DH-BCL2 was 6.8%. CNS relapses were early, predominantly leptomeningeal (73%), and co-occurred with systemic relapse (64%). High-risk CNS International Prognostic Index (CNS-IPI) and concordant bone marrow involvement were associated with an elevated CNS relapse risk in HGBCL-DH-BCL2. The “refined cell-of-origin” classification assigned 20% of DLBCL morphology tumors with germinal center B-cell–like phenotype (GCB-DLBCL) into a distinct subgroup based on DZsig expression (DZsig+). CNS relapse risk in DZsig+ (2 year: 6.4%) was independent of HGBCL-DH-BCL2 status and was further stratified by the CNS-IPI. CNS relapse in DZsig-negative GCB-DLBCL was rare (2-year risk, 1.4%; P = .04 vs DZsig+) and exclusively parenchymal. Altogether, the CNS relapse risk in HGBCL-DH-BCL2 is lower than previously reported, and DZsig refines risk stratification in GCB-DLBCL.

Article Details

Journal Blood
Volume / Issue Vol. 145, Issue 6
Published February 06, 2025
Pages 590-596
ISSN 0006-4971
Publisher Elsevier BV

Journal Info

Blood

Elsevier BV

ISSN: 0006-4971 Health Sciences

Authors (18)

W

Waleed Alduaij

1Centre for Lymphoid Cancer, BC Cancer, Vancouver, BC, Canada

A

Aixiang Jiang

1Centre for Lymphoid Cancer, British Columbia Cancer, Vancouver, BC, Canada

D

Diego Villa

8Division of Medical Oncology, BC Cancer Centre for Lymphoid Cancer and The University of British Columbia, Vancouver, Canada

B

Brett Collinge

1Centre for Lymphoid Cancer, BC Cancer, Vancouver, BC, Canada

S

Susana Ben-Neriah

1Centre for Lymphoid Cancer, British Columbia Cancer, Vancouver, BC, Canada

M

Merrill Boyle

1Centre for Lymphoid Cancer, British Columbia Cancer, Vancouver, BC, Canada

B

Barbara Meissner

1Centre for Lymphoid Cancer, British Columbia Cancer, Vancouver, BC, Canada

L

Laura K. Hilton

4Centre for Lymphoid Cancer, BC Cancer, Vancouver, BC, Canada

P

Pedro Farinha

6BC Cancer, Vancouver, BC, Canada

G

Graham W. Slack

6BC Cancer, Vancouver, BC, Canada

J

Jeffrey W. Craig

Department of Pathology University of Virginia Medical Center Charlottesville Virginia USA

A

Alina S. Gerrie

21BC Cancer Centre for Lymphoid Cancer, University of British Columbia, Vancouver, BC, Canada

C

Ciara L. Freeman

7Department of Blood and Marrow Transplant and Cellular Immunotherapy, H. Lee Moffitt Cancer Center and Research Institute, Tampa, FL

A

Andrew J. Mungall

5Canada’s Michael Smith Genome Sciences Centre, BC Cancer, Vancouver, BC, Canada

C

Christian Steidl

5Centre for Lymphoid Cancer, British Columbia Cancer, Vancouver, Canada

L

Laurie H. Sehn

8Division of Medical Oncology, BC Cancer Centre for Lymphoid Cancer and The University of British Columbia, Vancouver, Canada

D

David W. Scott

5Centre for Lymphoid Cancer, British Columbia Cancer, Vancouver, Canada

K

Kerry J. Savage

6BC Cancer, Vancouver, BC, Canada