Adrenal lipoma formation via PI(3,4,5)P <sub>3</sub> /AKT-dependent transdifferentiation of adrenocortical cells into adipocytes

S Shogo Yanai (Department of Biochemical Pathophysiology, Medical Research Laboratory, Institute of Integrated Research, Institute of Science Tokyo) J Junko Sasaki (Department of Biochemical Pathophysiology, Medical Research Laboratory, Institute of Integrated Research, Institute of Science Tokyo) H Hyeon-Cheol Lee-Okada (Department of Biochemistry, Juntendo University Graduate School of Medicine) F Fumiya Takahashi (Department of Molecular Biology, Graduate School of Medical Sciences, Kyushu University) Y Yuto Kikuchi (Department of Biochemical Pathophysiology, Medical Research Laboratory, Institute of Integrated Research, Institute of Science Tokyo) S Shin Morioka (Department of Biochemical Pathophysiology, Medical Research Laboratory, Institute of Integrated Research, Institute of Science Tokyo) T Toshiyoshi Yamamoto (Department of Biochemical Pathophysiology, Medical Research Laboratory, Institute of Integrated Research, Institute of Science Tokyo) K Katsuya Yuguchi (Department of Biochemical Pathophysiology, Medical Research Laboratory, Institute of Integrated Research, Institute of Science Tokyo) M Miko Oikawa (Department of Biochemical Pathophysiology, Medical Research Laboratory, Institute of Integrated Research, Institute of Science Tokyo) H Hiroaki Kajiho (Department of Biochemical Pathophysiology, Medical Research Laboratory, Institute of Integrated Research, Institute of Science Tokyo) T Takashi Baba (Department of Molecular Biology, Graduate School of Medical Sciences, Kyushu University) C Chikako Yokoyama (Department of Chemistry and Bioengineering, Graduate School of Engineering, Osaka Metropolitan University) K Ken-Ichirou Morohashi (Department of Internal Medicine, Kurume University School of Medicine) A Akira Suzuki (Division of Molecular and Cellular Biology, Kobe University Graduate School of Medicine) T Takehiko Yokomizo (Department of Biochemistry, Juntendo University Graduate School of Medicine) T Takehiko Sasaki (Department of Biochemical Pathophysiology, Medical Research Laboratory, Institute of Integrated Research, Institute of Science Tokyo)

Abstract

Adrenal lipomas are benign tumors containing ectopic adipose tissue in the adrenal gland, an organ that normally lacks both adipocytes and their progenitors. The origin of this ectopic fat remains enigmatic, and the absence of a genetic animal model has hindered its investigation. Phosphatidylinositol 3,4,5-trisphosphate [PI(3,4,5)P 3 ], a key signaling lipid that regulates cellular growth and differentiation, is tightly regulated by the lipid phosphatases PTEN (phosphatase and tensin homolog) and SHIP2 (SH2-containing inositol phosphatase 2). Here, we demonstrate that simultaneous loss of Pten and Ship2 in the adrenal cortex induces adrenal lipoma formation in mice. These lipomatous cells display both adipocyte-like morphology and adipocyte-specific gene expression. Lineage tracing revealed that these lipomas originate from the adrenal cortex. Mechanistically, PI(3,4,5)P 3 hyperaccumulation in the adrenal cortex activates AKT (AKT8 virus oncogene cellular homolog), leading to ectopic PPARγ (peroxisome proliferator activated receptor gamma) expression, a key driver of adipocyte differentiation. This study suggests that the PI(3,4,5)P 3 /AKT-driven transdifferentiation of adrenocortical cells may represent a central mechanism underlying adrenal lipoma formation, thereby providing insights into lipoma pathogenesis and cellular reprogramming in vivo.

Article Details

Volume / Issue Vol. 122, Issue 37
Published September 16, 2025
ISSN 0027-8424
Publisher National Academy of Sciences

Authors (16)

S

Shogo Yanai

Department of Biochemical Pathophysiology, Medical Research Laboratory, Institute of Integrated Research, Institute of Science Tokyo

J

Junko Sasaki

Department of Biochemical Pathophysiology, Medical Research Laboratory, Institute of Integrated Research, Institute of Science Tokyo

H

Hyeon-Cheol Lee-Okada

Department of Biochemistry, Juntendo University Graduate School of Medicine

F

Fumiya Takahashi

Department of Molecular Biology, Graduate School of Medical Sciences, Kyushu University

Y

Yuto Kikuchi

Department of Biochemical Pathophysiology, Medical Research Laboratory, Institute of Integrated Research, Institute of Science Tokyo

S

Shin Morioka

Department of Biochemical Pathophysiology, Medical Research Laboratory, Institute of Integrated Research, Institute of Science Tokyo

T

Toshiyoshi Yamamoto

Department of Biochemical Pathophysiology, Medical Research Laboratory, Institute of Integrated Research, Institute of Science Tokyo

K

Katsuya Yuguchi

Department of Biochemical Pathophysiology, Medical Research Laboratory, Institute of Integrated Research, Institute of Science Tokyo

M

Miko Oikawa

Department of Biochemical Pathophysiology, Medical Research Laboratory, Institute of Integrated Research, Institute of Science Tokyo

H

Hiroaki Kajiho

Department of Biochemical Pathophysiology, Medical Research Laboratory, Institute of Integrated Research, Institute of Science Tokyo

T

Takashi Baba

Department of Molecular Biology, Graduate School of Medical Sciences, Kyushu University

C

Chikako Yokoyama

Department of Chemistry and Bioengineering, Graduate School of Engineering, Osaka Metropolitan University

K

Ken-Ichirou Morohashi

Department of Internal Medicine, Kurume University School of Medicine

A

Akira Suzuki

Division of Molecular and Cellular Biology, Kobe University Graduate School of Medicine

T

Takehiko Yokomizo

Department of Biochemistry, Juntendo University Graduate School of Medicine

T

Takehiko Sasaki

Department of Biochemical Pathophysiology, Medical Research Laboratory, Institute of Integrated Research, Institute of Science Tokyo