A comprehensive genetic study of classic Hodgkin lymphoma using circulating tumor DNA

M Maria Cristina Pirosa (1Clinic of Hematology, Oncology Institute of Southern Switzerland, Ente Ospedaliero Cantonale, Bellinzona, Switzerland) A Alessio Bruscaggin (Institute of Oncology Research, Bellinzona, Switzerland) L Lodovico Terzi di Bergamo (Institute of Oncology Research, Bellinzona, Switzerland) M Matin Salehi (3Laboratory of Experimental Hematology, Institute of Oncology Research, Bellinzona, Switzerland) F Federico Jauk (4Institute of Oncology Research, Bellinzona, Switzerland) G Gabriela Forestieri (Institute of Oncology Research, Bellinzona, Switzerland) S Simone Bocchetta (1Laboratory of Experimental Hematology, Institute of Oncology Research, Bellinzona, Switzerland) D Deborah Piffaretti (1Laboratory of Experimental Hematology, Institute of Oncology Research, Bellinzona, Switzerland) R Riccardo Moia (32Division of Hematology, Department of Translational Medicine, University of Eastern Piedmont, Novara, Italy) V Vanessa Cristaldi (7Department of Biomedical Sciences, Humanitas University, Milan, Italy) M Martina di Trani (7Department of Biomedical Sciences, Humanitas University, Milan, Italy) G Georgia Alice Galimberti (1Laboratory of Experimental Hematology, Institute of Oncology Research, Bellinzona, Switzerland) K Katia Pini (1Laboratory of Experimental Hematology, Institute of Oncology Research, Bellinzona, Switzerland) V Valeria Spina (1Laboratory of Experimental Hematology, Institute of Oncology Research, Bellinzona, Switzerland) C Claudia Giordano (8Department of Clinical Medicine and Surgery, Federico II University Medical School, Naples, Italy) A Adalgisa Condoluci (1Laboratory of Experimental Hematology, Institute of Oncology Research, Bellinzona, Switzerland) I Ilaria Romano (37Oncology Institute of Southern Switzerland, Bellinzona, Switzerland) S Salvatore Annunziata (9UOC Medicina Nucleare, GSTeP Radiopharmacy TracerGLab, Fondazione Policlinico Universitario A. Gemelli IRCCS, Rome, Italy) F Fabrizio Bergesio (2Santa Croce e Carle General Hospital, Cuneo, Italy) R Renzo Boldorini (11Pathology Department, Ospedale Maggiore della Carità, University of Eastern Piedmont, Novara, Italy) E Eugenio Borsatti (12Nuclear Medicine, Centro di Riferimento Oncologico, Aviano, Italy) P Pietro Bulian (13Clinical and Experimental Onco Hematology Unit, Centro di Riferimento Oncologico, Aviano, Italy) E Eleonora Calabretta (1Department of Medical Oncology, Dana-Farber Cancer Institute, Boston, United States) S Stephane Chauvie (2Santa Croce e Carle General Hospital, Cuneo, Italy) F Francesco Corrado (9Center for Early Detection and Interception, Medical Oncology, Dana-Farber Cancer Institute, Boston, MA) S Stefania Crisci (14Hematology-Oncology and Stem Cell Transplantation Unit, Istituto Nazionale Tumori-IRCCS-Fondazione “G. Pascale,” Naples, Italy) M Marco Cuzzocrea (15Clinic of Nuclear Medicine and Molecular Imaging, Imaging Institute of Southern Switzerland, Bellinzona, Switzerland) R Rosaria De Filippi (8Department of Clinical Medicine and Surgery, Federico II University Medical School, Naples, Italy) B Bernhard Gerber (2Clinic of Hematology, Oncology Institute of Southern Switzerland, Ente Ospedaliero Cantonale, Bellinzona, Switzerland) M Michał Kurlapski (16Department of Hematology and Bone Marrow Transplantation, Medical University of Gdańsk, Gdańsk, Poland) L Luigi Maria Larocca (17Division of Pathology, Fondazione Policlinico Universitario Agostino Gemelli, Catholic University of the Sacred Heart, Rome, Italy) E Elisabetta Merlo (18Division of Pathology, Ente Ospedaliero Cantonale, Locarno, Switzerland) A Andrea Rinaldi M Marcello Rodari (20Unit of Nuclear Medicine, Humanitas Research Hospital, Milan, Italy) G Grzegorz Romanowicz (21Department of Nuclear Medicine, Medical University of Gdańsk, Gdańsk, Poland) G Gian Mauro Sacchetti (22Nuclear Medicine, Ospedale Maggiore della Carità, Novara, Italy) A Anastasios Stathis (Oncology Institute of Southern Switzerland, Ente Ospedaliero Cantonale, Bellinzoona, Switzerland) G Georg Stussi (Oncology Institute of Southern Switzerland, Bellinzona, Switzerland) I Ilaria Zangrilli (23Department of Diagnostic Imaging, Oncological Radiotherapy and Hematology, Fondazione Policlinico Universitario Agostino Gemelli, Rome, Italy) A Antonello Pinto (15Istituto Nazionale Tumori, IRCCS-Fondazione “G. Pascale”, Naples, Italy) L Luca Mazzucchelli (Ente Ospedaliero Cantonale, Istituto Cantonale di Patologia) V Valter Gattei (3Clinical and Experimental Onco-Hematology Unit, Centro di Riferimento Oncologico di Aviano, Istituto di Ricovero e Cura a Carattere Scientifico, Aviano, Italy) J Jan Maciej Zaucha A Armando Santoro (IRCCS Humanitas Research Hospital, Milan) S Stefan Hohaus (14Fondazione Policlinico Universitario A. Gemelli IRCCS, Rome, Italy) F Franco Cavalli (2Institute of Oncology Research, Bellinzona, Switzerland) A Alexandar Tzankov C Carmelo Carlo-Stella (3Humanitas University and IRCCS Humanitas Research Hospital, Milan, Italy) G Gianluca Gaidano (13Department of Translational Medicine, University of Eastern Piedmont, Novara, Italy) L Luca Ceriani (2Institute of Oncology Research, Bellinzona, Switzerland) E Emanuele Zucca (Institute of Oncology Research, Bellinzona, Switzerland) D Davide Rossi (Institute of Oncology Research, Bellinzona, Switzerland)

Abstract

Abstract This study analyzed the genetics of classic Hodgkin lymphoma (cHL) by using circulating tumor DNA (ctDNA). Two genetic subtypes were identified, differing in genetic instability mechanisms: one subtype (64% of cases) showed a higher mutation load and a higher fraction of mutations associated with activation-induced cytidine deaminase and microsatellite instability signatures, whereas the other subtype (36% of cases) exhibited chromosomal instability with more somatic copy number alterations. Whole-genome duplication was more common in cHL compared with other B-cell tumors and emerged as a prognostic biomarker for patients undergoing Adriamycin (doxorubicin)-bleomycin-vinblastine-dacarbazine–based therapy. Noncoding regulatory mutations, similar to those in diffuse large B-cell lymphoma, were highly prevalent in 86% of cHL. A recurrent somatic expression quantitative trait locus (seQTL) involving the BCL6 gene was found in 30% of cases. The seQTL of BCL6 aligned with accessible chromatin and increased H3K27 acetylation in cHL, disrupted PRDM1 binding, and co-occurred with BCL6 expression in cHL cells. Weak to strong expression of BCL6 was observed in 68% of cases, and BCL6 expression associated with gene repression similarly in cHL and germinal center B cells. After BCL6 degradation, the core set of genes directly bound and regulated by BCL6 was derepressed in cHL, and proliferation was impaired. The number and clonality of neoantigens was associated with tumor microenvironment type and response to checkpoint blockade. Finally, ctDNA analysis was suggested as a tool to distinguish ambiguous positron emission tomography/computed tomography–positive lesions after treatment.

Article Details

Journal Blood
Volume / Issue Vol. 146, Issue 10
Published September 04, 2025
Pages 1207-1224
ISSN 0006-4971
Publisher Elsevier BV

Journal Info

Blood

Elsevier BV

ISSN: 0006-4971 Health Sciences

Authors (52)

M

Maria Cristina Pirosa

1Clinic of Hematology, Oncology Institute of Southern Switzerland, Ente Ospedaliero Cantonale, Bellinzona, Switzerland

A

Alessio Bruscaggin

Institute of Oncology Research, Bellinzona, Switzerland

L

Lodovico Terzi di Bergamo

Institute of Oncology Research, Bellinzona, Switzerland

M

Matin Salehi

3Laboratory of Experimental Hematology, Institute of Oncology Research, Bellinzona, Switzerland

F

Federico Jauk

4Institute of Oncology Research, Bellinzona, Switzerland

G

Gabriela Forestieri

Institute of Oncology Research, Bellinzona, Switzerland

S

Simone Bocchetta

1Laboratory of Experimental Hematology, Institute of Oncology Research, Bellinzona, Switzerland

D

Deborah Piffaretti

1Laboratory of Experimental Hematology, Institute of Oncology Research, Bellinzona, Switzerland

R

Riccardo Moia

32Division of Hematology, Department of Translational Medicine, University of Eastern Piedmont, Novara, Italy

V

Vanessa Cristaldi

7Department of Biomedical Sciences, Humanitas University, Milan, Italy

M

Martina di Trani

7Department of Biomedical Sciences, Humanitas University, Milan, Italy

G

Georgia Alice Galimberti

1Laboratory of Experimental Hematology, Institute of Oncology Research, Bellinzona, Switzerland

K

Katia Pini

1Laboratory of Experimental Hematology, Institute of Oncology Research, Bellinzona, Switzerland

V

Valeria Spina

1Laboratory of Experimental Hematology, Institute of Oncology Research, Bellinzona, Switzerland

C

Claudia Giordano

8Department of Clinical Medicine and Surgery, Federico II University Medical School, Naples, Italy

A

Adalgisa Condoluci

1Laboratory of Experimental Hematology, Institute of Oncology Research, Bellinzona, Switzerland

I

Ilaria Romano

37Oncology Institute of Southern Switzerland, Bellinzona, Switzerland

S

Salvatore Annunziata

9UOC Medicina Nucleare, GSTeP Radiopharmacy TracerGLab, Fondazione Policlinico Universitario A. Gemelli IRCCS, Rome, Italy

F

Fabrizio Bergesio

2Santa Croce e Carle General Hospital, Cuneo, Italy

R

Renzo Boldorini

11Pathology Department, Ospedale Maggiore della Carità, University of Eastern Piedmont, Novara, Italy

E

Eugenio Borsatti

12Nuclear Medicine, Centro di Riferimento Oncologico, Aviano, Italy

P

Pietro Bulian

13Clinical and Experimental Onco Hematology Unit, Centro di Riferimento Oncologico, Aviano, Italy

E

Eleonora Calabretta

1Department of Medical Oncology, Dana-Farber Cancer Institute, Boston, United States

S

Stephane Chauvie

2Santa Croce e Carle General Hospital, Cuneo, Italy

F

Francesco Corrado

9Center for Early Detection and Interception, Medical Oncology, Dana-Farber Cancer Institute, Boston, MA

S

Stefania Crisci

14Hematology-Oncology and Stem Cell Transplantation Unit, Istituto Nazionale Tumori-IRCCS-Fondazione “G. Pascale,” Naples, Italy

M

Marco Cuzzocrea

15Clinic of Nuclear Medicine and Molecular Imaging, Imaging Institute of Southern Switzerland, Bellinzona, Switzerland

R

Rosaria De Filippi

8Department of Clinical Medicine and Surgery, Federico II University Medical School, Naples, Italy

B

Bernhard Gerber

2Clinic of Hematology, Oncology Institute of Southern Switzerland, Ente Ospedaliero Cantonale, Bellinzona, Switzerland

M

Michał Kurlapski

16Department of Hematology and Bone Marrow Transplantation, Medical University of Gdańsk, Gdańsk, Poland

L

Luigi Maria Larocca

17Division of Pathology, Fondazione Policlinico Universitario Agostino Gemelli, Catholic University of the Sacred Heart, Rome, Italy

E

Elisabetta Merlo

18Division of Pathology, Ente Ospedaliero Cantonale, Locarno, Switzerland

A

Andrea Rinaldi

M

Marcello Rodari

20Unit of Nuclear Medicine, Humanitas Research Hospital, Milan, Italy

G

Grzegorz Romanowicz

21Department of Nuclear Medicine, Medical University of Gdańsk, Gdańsk, Poland

G

Gian Mauro Sacchetti

22Nuclear Medicine, Ospedale Maggiore della Carità, Novara, Italy

A

Anastasios Stathis

Oncology Institute of Southern Switzerland, Ente Ospedaliero Cantonale, Bellinzoona, Switzerland

G

Georg Stussi

Oncology Institute of Southern Switzerland, Bellinzona, Switzerland

I

Ilaria Zangrilli

23Department of Diagnostic Imaging, Oncological Radiotherapy and Hematology, Fondazione Policlinico Universitario Agostino Gemelli, Rome, Italy

A

Antonello Pinto

15Istituto Nazionale Tumori, IRCCS-Fondazione “G. Pascale”, Naples, Italy

L

Luca Mazzucchelli

Ente Ospedaliero Cantonale, Istituto Cantonale di Patologia

V

Valter Gattei

3Clinical and Experimental Onco-Hematology Unit, Centro di Riferimento Oncologico di Aviano, Istituto di Ricovero e Cura a Carattere Scientifico, Aviano, Italy

J

Jan Maciej Zaucha

A

Armando Santoro

IRCCS Humanitas Research Hospital, Milan

S

Stefan Hohaus

14Fondazione Policlinico Universitario A. Gemelli IRCCS, Rome, Italy

F

Franco Cavalli

2Institute of Oncology Research, Bellinzona, Switzerland

A

Alexandar Tzankov

C

Carmelo Carlo-Stella

3Humanitas University and IRCCS Humanitas Research Hospital, Milan, Italy

G

Gianluca Gaidano

13Department of Translational Medicine, University of Eastern Piedmont, Novara, Italy

L

Luca Ceriani

2Institute of Oncology Research, Bellinzona, Switzerland

E

Emanuele Zucca

Institute of Oncology Research, Bellinzona, Switzerland

D

Davide Rossi

Institute of Oncology Research, Bellinzona, Switzerland